Immunology · Year 2 · from Immunology

Case 1: Severe Combined Immunodeficiency (SCID)

Patient Demographics

  • Age: 4 months old
  • Sex: Male
  • Ethnicity: Caucasian

Chief Complaint

Failure to thrive and recurrent infections

History of Present Illness

A 4-month-old male infant is referred to pediatric immunology after being hospitalized for Pneumocystis jirovecii pneumonia (PJP). He has had persistent oral thrush since 2 weeks of age despite multiple courses of nystatin. His mother reports chronic diarrhea and poor weight gain. He was born full-term with no complications. Newborn screening was not available for SCID in his birth state.

Past Medical History

  • Oral thrush since 2 weeks of age
  • Chronic diarrhea starting at 2 months
  • Admitted twice for respiratory infections
  • Pneumocystis jirovecii pneumonia (current)

Birth History

  • Full-term, uncomplicated vaginal delivery
  • Birth weight: 3.4 kg (50th percentile)
  • No newborn SCID screening performed

Family History

  • Parents are non-consanguineous
  • Maternal uncle died at 5 months of age from "lung infection"

Physical Examination

  • General: Wasted, ill-appearing infant, visibly malnourished
  • Vital Signs: T 38.2C, HR 160, RR 55, SpO2 88% on room air
  • Weight: 4.5 kg (<3rd percentile, was 50th at birth)
  • HEENT: Oral thrush coating tongue and buccal mucosa, NO visible tonsils
  • Lymphatics: NO palpable lymph nodes
  • Lungs: Bilateral crackles, increased work of breathing
  • Abdomen: No hepatosplenomegaly
  • Skin: No rashes, no evidence of graft-versus-host disease

Laboratory Workup

TestResultReference Range
WBC3,200/uL6,000-17,500/uL
Absolute lymphocyte count200/uL3,000-9,500/uL
CD3+ T cells15/uL2,500-5,600/uL
CD4+ T cells8/uL1,600-4,000/uL
CD8+ T cells5/uL560-1,700/uL
CD19+ B cells850/uL300-2,000/uL
CD16+56+ NK cells8/uL170-1,100/uL
IgG180 mg/dL (maternal)141-930 mg/dL
IgA<5 mg/dL8-74 mg/dL
IgM<10 mg/dL26-210 mg/dL
TREC levelsUndetectablePresent
Genetic testingIL2RG mutation--

Clinical Image

Image source: Wikimedia Commons (https://commons.wikimedia.org/wiki/File:Human_tongue_infected_with_oral_candidiasis.jpg). Public domain.

Diagnosis

X-linked Severe Combined Immunodeficiency (X-SCID) due to IL2RG (common gamma chain) mutation, presenting with T-B+NK- phenotype.

Discussion

SCID represents the most severe form of primary immunodeficiency, characterized by profound defects in T cell development. X-linked SCID is caused by mutations in IL2RG, which encodes the common gamma chain shared by receptors for IL-2, IL-4, IL-7, IL-9, IL-15, and IL-21. IL-7 signaling is essential for T cell development, and IL-15 is required for NK cell development, explaining the T-B+NK- phenotype. B cells develop but cannot function without T cell help.

Key features distinguishing this case:

  • Profound lymphopenia with markedly reduced T cells
  • Absent T cell and NK cells with preserved B cell numbers (T-B+NK-)
  • Opportunistic infection (PJP) indicates severe cellular immunodeficiency
  • Maternal uncle's death suggests X-linked inheritance
  • Absent lymphoid tissue (tonsils, lymph nodes)

Treatment

  1. Immediate: Treat PJP with TMP-SMX, prophylaxis against infections, IVIG replacement
  2. Isolation: Strict infection precautions, avoid live vaccines
  3. Definitive therapy: Hematopoietic stem cell transplantation (HSCT) - outcomes are best when performed before 3.5 months of age and before infections develop
  4. Gene therapy: Now FDA-approved for X-SCID as an alternative to HSCT

Note: This case highlights the importance of newborn SCID screening using the TREC assay, now universal in all US states.


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